Mycetoma is a chronic granulomatous disease that can be debilitating, increasing the healthcare burden of patients and their families. It is caused by fungal or filamentous bacterial infection. Mycetoma usually develops in farmers after a traumatic inoculation of the organism into the subcutaneous tissue, muscle or tendon. The foot is the most commonly affected site. The leg and upper extremities including the neck, chest and shoulder can also be involved with decreasing incidence. The ‘dot-in-circle’ sign is a classical feature on magnetic resonance imaging (MRI). We presented a case of shoulder mycetoma, a rare site of infection that showed the ‘dot-in-circle’ sign on MRI. Micro- scopically, it exhibited multiple granulomatous inflammations surrounded by abundant foamy macrophages. The fungal elements were highlighted using Gomori methenamine silver stain.